FIBROMYALGIA:
ABSTRACTS FROM
SELECTED JOURNAL ARTICLES, 1999
The abstracts in this collection are intended to provide health
professionals and patients with a convenient overview of trends in research on
fibromyalgia published in medical journals in the year 1999. The studies were
selected from the extensive literature on fibromyalgia so as to cover a wide
range of subjects in limited space. The abstacts are arranged in alphabetical
order by lead author.
Similar collections of abstracts published in 2000 and 2001 can be
found on the website of the National Fibromyalgia Partnership:
www.fmpartnership.org.
Adler GK, Kinsley BT, Hurwitz S, Mossey CJ, Goldenberg DL
Reduced hypothalamic-pituitary and sympathoadrenal responses to
hypoglycemia in women with fibromyalgia syndrome
PURPOSE: To
perform a detailed comparison of the hypothalamic-pituitary-adrenal axis and
the sympathoadrenal system in women with and without fibromyalgia. SUBJECTS AND METHODS: Fifteen premenopausal women
who met the 1990 American College of Rheumatology criteria for the diagnosis of
fibromyalgia and 13 healthy, premenopausal women were enrolled. We measured
baseline 24-hour urinary free cortisol levels and evening and morning
adrenocorticotropic hormone (ACTH) and
cortisol levels, performed stepped hypoglycemic hyperinsulinemic clamp studies
in which serum glucose levels were decreased from 5.0 to 2.2 mmol/L, and
compared the effects of infusions of placebo and ACTH. RESULTS: Women with fibromyalgia had normal 24-hour
urinary free cortisol levels and normal diurnal patterns of ACTH and cortisol. There was a
significant, approximately 30%, reduction in the ACTH and epinephrine responses to hypoglycemia in women
with fibromyalgia compared with controls. Prolactin, norepinephrine, cortisol,
and dehydroepiandrosterone responses to hypoglycemia were similar in the two
study groups. In subjects with fibromyalgia, the epinephrine response to
hypoglycemia correlated (p=0.01) inversely with overall health status as
measured by the fibromyalgia impact questionnaire. Graded ACTH infusion revealed similar
increases in cortisol in women with fibromyalgia and healthy controls. CONCLUSIONS: Patients with fibromyalgia
have an impaired ability to activate the hypothalamic-pituitary portion of the
hypothalamic pituitary-adrenal axis as well as the sympathoadrenal system,
leading to reduced ACTH and
epinephrine responses to hypoglycemia.
Am J Med 1999 May; 106(5):534-43
Bennett RM
Disordered growth hormone secretion in fibromyalgia: a review of recent
findings and an hypothesized etiology
Growth hormone (GH) deficiency
occurs in about 30% of fibromyalgia patients. Treatment of GH deficient fibromyalgia
patients with recombinant growth hormone improves several clinical features,
including the tender point count. Defective GH secretion in these patients appears to be due to increased somatostatin
tone in the hypothalamus. An hypothesis is presented which relates
dysfunctional GH
secretion to
the effects of intermittent hypercortisolemia on upregulating the density of
beta-adrenergic receptors in the hypothalamus. The resulting augmentation of
beta-adrenergic tone stimulates the release of somatostatin, thus impairing GH secretion.
Z Rheumatol 1998; 57 Suppl 2:72-6
Bennett RM
Emerging concepts in the neurobiology of chronic pain: evidence of
abnormal sensory processing in fibromyalgia
Chronic pain often differs from acute pain.
The correlation between tissue pathology and the perceived severity of the
chronic pain experience is poor or even absent. Furthermore, the sharp spatial
localization of acute pain is not a feature of chronic pain; chronic pain is
more diffuse and often spreads to areas beyond the original site. Of
importance, chronic pain seldom responds to the therapeutic measures that are successful
in treating acute pain. Physicians who are unaware of these differences may
label the patient with chronic pain as being neurotic or even a malingerer.
During the past decade, an exponential growth has occurred in the scientific
underpinnings of chronic pain states. In particular, the concept of non-nociceptive
pain has been refined at a physiologic, structural, and molecular level. This
review focuses on this new body of knowledge, with particular reference to the
chronic pain state termed “fibromyalgia.”
Mayo Clin Proc 1999 Apr; 74(4):38-98
Berman BM, Swyers JP
Complementary medicine treatments for fibromyalgia syndrome
Fibromyalgia is a chronic-pain-related syndrome associated with high
rates of complementary and alternative medicine (CAM) use. Among the many CAM therapies frequently used by fibromyalgia patients,
empirical research data exist to support the use of only three: (1) mind-body,
(2) acupuncture, and (3) manipulative therapies for treating fibromyalgia.
The strongest data exist for the use of mind-body techniques (e.g. biofeedback,
hypnosis, cognitive behavioral therapy), particularly when utilized as part of
a multidisciplinary approach to treatment. The weakest data exist for
manipulative techniques (e.g., chiropractic and massage). The data supporting
the use of acupuncture for fibromyalgia are only moderately strong. Also, for
some fibromyalgia patients, acupuncture can exacerbate symptoms, further complicating
its application for this condition. Further research is needed not only in
these three areas, but also for other treatments being frequently utilized by
fibromyalgia patients.
Baillieres Best Pract Res Clin Rheumatol 1999 Sep; 13(3):487-92
Breau LM, McGrath PJ, Ju LH
This article reviews the current literature
on childhood fibromyalgia and chronic fatigue syndrome. In doing so, it
questions assumptions about the presumed nature of the disorders--that they are
distinct from each other and are duplicates of their adult counterparts. It
also attempts to synthesize the available data to reach some preliminary
judgments about these disorders: that fibromyalgia and chronic fatigue syndrome
may be related in children and may not be duplicates of the adult disorders;
that psychological and psychosocial factors are unlikely contributors to the
etiology of these disorders; and that the evidence is increasingly pointing to
a role for genetic factors in their etiology. A discussion of the research into
treatments for childhood fibromyalgia and chronic fatigue syndrome highlights
the lack of well-designed, controlled studies. Finally, directions for future
research are offered where results of the current literature are unclear.
J Dev Behav Pediatr 1999 Aug; 20(4):278-88
Buskila D
Because
of the lack of understanding of the basis of fibromyalgia, therapy remains
empiric. This article reviews the different drug elements used in fibromyalgia,
including psychotropic agents (anti-depressants, sedatives and hypnotics),
anti-inflammatories, analgesics and other pharmacological compounds. The
strength of evidence for the therapeutic effect of each medicinal modality is
presented, with the emphasis on results of randomized controlled trials. The
importance of the expected effects of the current drug modalities, and whether
these drugs have short- or long-term effects, are also discussed. Future
directions, including testing of newer antidepressants, analgesics and
non-steroidal anti-inflammatory drugs (Cox-2 selective inhibitors), as well as
the need for long-term comparative trials of both drug efficacy and toxicity,
are discussed.
Baillieres Best Pract Res Clin Rheumatol 1999 Sep; 13(3):479-85
Crofford LJ
The hypothalamic-pituitary-adrenal stress axis in fibromyalgia and
chronic fatigue syndrome
HPA axis
abnormalities in FM,
CFS, and other
stress-related disorders must be placed in a broad clinical context. We know
that interventions providing symptomatic improvement in patients with FM and CFS can directly or indirectly
affect the HPA axis. These interventions
include exercise, tricyclic anti-depressants, and serotonin reuptake
inhibitors. There is little direct information as to how the specific HPA axis perturbations seen in FM can be related to the major
symptomatic manifestations of pain, fatigue, sleep disturbance, and
psychological distress. Since many of these somatic and psychological symptoms
are present in other syndromes that exhibit HPA axis disturbances, it seems reasonable to suggest that there may be
some relationship between basal and dynamic function of the HPA axis and clinical
manifestations of FM
and CFS.
Z Rheumatol 1998; 57 Suppl 2:67-71
Dessein PH, Shipton EA, Joffe BI, Hadebe DP, Stanwix AE, Van der Merwe
BA
Hyposecretion
of adrenal androgens and the relation of serum adrenal steroids, serotonin and
insulin-like growth factor-1 to clinical features in women with fibromyalgia
Neuroendocrine deficiencies have been implicated in fibromyalgia (FM). In the present study, adrenal
androgen metabolites and their relationship with health status in FM were investigated. For
comparison, serum levels of other implicated neuroendocrine mediators were
correlated with health status. Fifty-seven consecutive women with FM completed the Fibromyalgia
Impact Questionnaire (FIQ). Fasting
blood samples were taken for measurement of dehydroepiandrosterone sulphate (DHEAS), free testosterone (T), cortisol, serotonin and
insulin-like growth factor-1. Normal value for DHEAS and T were
obtained from 114 controls. DHEAS levels
were decreased significantly in pre- and postmenopausal patients (p<0.000l
and p<0.0005, respectively). T levels were decreased significantly in premenopausal and
insignificantly in postmenopausal patients (p<0.0001 and p=0.06,
respectively). The following correlations between neurohormonal levels and FIQ scores were found: DHEAS (after adjustment for age)
vs. pain (p < 0.001) and T (after adjustment for age)
versus physical functioning (p=0.002). None of the other neurohormonal
levels correlated significantly with any of the FIQ scores. IGF-1 levels were lower in the obese patients as compared
to those who were non-obese (p=0.03). The BMI correlated positively with pain (p<0.001) and inversely with DHEAS levels (p=0.006). After
further adjustment for BMI, the
correlation between age adjusted DHEAS and pain was no longer significant. Hyposecretion of
adrenal androgens was documented in FM. This was more pronounced in obese patients. Low serum androgen levels
correlated with poor health status in FM. Longitudinal studies are needed to elucidate whether
these are cause and/or effect relationships.
Pain 1999
Nov; 83(2):313-9
Giovengo SL, Russell IJ, Larson AA
Increased concentrations of nerve growth factor in cerebrospinal fluid
of patients with fibromyalgia
OBJECTIVE: To
determine whether there is a difference in the concentration of nerve growth
factor (NGF) in the cerebrospinal fluid (CSF) from patients diagnosed with
primary fibromyalgia syndrome (FM), fibromyalgia
associated with other secondary conditions (SFM), patients with other painful conditions but lacking
fibromyalgia (OTHER),
and healthy
controls. METHODS:
The clinical
measures of pain threshold included the tender point index, a measure of pain
threshold intensity measured by digital pressure, and the average pain
threshold measured by dolorimetry. Concentrations of NGF in the CSF were measured using a 2-site
enzyme immunoassay. RESULTS: The
mean (+/- SEM)
concentration of NGF measured in patients with FM was significantly increased (41.8 +/- 12.7 pg/ml) compared to controls (9.1 +/- 4.1 pg/ml), but with large
variability. Concentrations of NGF in SFM (8.9 +/- 4.4 pg/ml) and OTHER (16.2 +/- 8.4 pg/ml) were
not elevated compared to controls. CONCLUSION: The findings of increased concentrations of NGF in patients with FM suggest that a central
mechanism, involving abnormalities in neuropeptides such as NGF, may be a factor in the
pathogenesis of FM.
J Rheumatol 1999 Jul; 26(7):1564-9
Grace GM, Nielson WR, Hopkins MA, Berg MA
Concentration and memory deficits in patients with fibromyalgia
syndrome
The present study compared 30 patients with fibromyalgia syndrome (FS) to 30 healthy control
subjects matched for age, sex, and estimated intellectual level on standardized
measures of attention, concentration, and memory as well as subjective ratings
of memory abilities and sleep quality. In addition, in order to investigate the
relationship between cognitive functioning and other physical and
psychological symptoms, subjects with FS completed psychological measures of pain severity, trait anxiety, and
depression. Results indicated that patients with FS performed more poorly on tests of immediate and
delayed recall, and sustained auditory concentration, and their ratings of both
their memory abilities and sleep quality were lower than those of controls.
Furthermore, perceived memory deficits of the FS subjects were disproportionately greater than their
objective deficits. Results indicated significant correlations between performance
on memory and concentration measures and scores on questionnaires of pain
severity and trait anxiety. Implications of these results for multidisciplinary
treatment programs are discussed.
Clin Exp Neuropsychol 1999 Aug; 21(4):477-87
Heim C, Ehlert U, Hellhammer DH
The potential role of hypocortisolism in the pathophysiology of
stress-related bodily disorders
Representing a challenge for current concepts of stress research, a
number of studies have now provided convincing evidence that the adrenal gland
is hypoactive in some stress-related states. The phenomenon of hypocortisolism
has mainly been described for patients who experienced a traumatic event and
subsequently developed post-traumatic stress disorder (PTSD). However, as presented in this
review, hypocortisolism does not merely represent a specific correlate of PTSD, since similar findings have
been reported for healthy individuals living under conditions of chronic stress
as well as for patients with several bodily disorders. These include chronic
fatigue syndrome, fibromyalgia, other somatoform disorders, rheumatoid
arthritis, and asthma, and many of these disorders have been related to stress.
Although hypocortisolism appears to be a frequent and widespread phenomenon,
the nature of the underlying mechanisms and the homology of these mechanisms
within and across clinical groups remain speculative. Potential mechanisms
include dysregulations on several levels of the hypothalamic-pituitary-adrenal
axis. In addition, factors such as genetic vulnerability, previous stress
experience, coping and personality styles may determine the manifestation of
this neuroendocrine abnormality. Several authors proposed theoretical
concepts on the development or physiological meaning of hypocortisolism. Based
on the reviewed findings, we propose that a persistent lack of cortisol
availability in traumatized or chronically stressed individuals may promote an
increased vulnerability for the development of stress-related bodily disorders.
This pathophysiological model may have important implications for the
prevention, diagnosis and treatment of the classical psychosomatic disorders.
Psychoneuroendocrinology 2000 Jan; 25(1): 1-35
Hodgson MJ, Kipen HM
Gulf War illnesses: causation and treatment
Soldiers returning from the Gulf War in 1991 described a range of
symptoms, including some consistent with the chronic fatigue syndrome,
fibromyalgia, and multiple chemical sensitivity. Well-defined adverse health
events attributable to service in the Gulf occurred. However, controlled
epidemiological studies in Gulf War veterans and controls describe significant
excesses of symptoms that were not clearly associated with pathologic disease.
At least 12% of veterans currently receive some form of disability from the
Department of Veterans Affairs [USA]. A
number of reports outline theories proposed to explain the excess, but few are
scientifically supported. Management guidelines for this spectrum of disorders
resembles that of many of “emerging overlap syndromes,” including multiple
chemical sensitivity, chronic fatigue syndrome, and fibromyalgia. They include
the establishment of a trusting doctor-patient relationship, negotiations
around a common ground of scientific and etiologic beliefs, non-labeling of the
disorder, and work toward recovery in the absence of clear etiologic answers.
J Occup
Environ Med 1999
Jun; 41(6):443-52
Korszun A, Sackett-Lundeen L, Papadopoulos E, Brucksch C, Masterson L,
Engelberg NC, Haus E, Demitrack MA, Crofford L
Melatonin levels in women with fibromyalgia and chronic fatigue
syndrome
OBJECTIVE: Fibromyalgia
(FM) and chronic fatigue syndrome
(CFS) are stress-associated
disorders mainly affecting women. FM is characterized primarily by widespread musculoskeletal pain, and CFS by profound debilitating
fatigue, but there is considerable overlap of clinical symptoms between these 2
syndromes. Neuroendocrine abnormalities have been noted in both FM and CFS, and desynchronization of
circadian systems has been postulated in their etiology. The pineal hormone
melatonin is involved in synchronizing circadian systems, and the use of
exogenous melatonin has become widespread in patients with FM and CFS. METHODS: We examined the
characteristics and relationship of melatonin and cortisol levels in
premenopausal women with FM (N=9) or
CFS (N=8), compared to age and
menstrual cycle phase matched controls. Blood was collected from an indwelling
intravenous catheter every 10 min over 24 h, and plasma melatonin and cortisol
were determined by radioimmunoassay at 60 and 10 min intervals, respectively. RESULTS: Night-time (23:00-06:50)
plasma melatonin levels were significantly higher in FM patients compared to
controls (p <0.05), but there was no
significant difference in melatonin levels between CFS patients and controls. No
differences in the timing of cortisol and melatonin secretory patterns and no
internal desynchronization of the 2 rhythms were found in either patient
group, compared to controls. CONCLUSION: Raised plasma melatonin concentrations have been documented in several
other conditions that are associated with dysregulation of neuroendocrine axes.
Increased melatonin levels may represent a marker of increased susceptibility
to stress-induced hypothalamic disruptions. These data indicate that there is
no rationale for melatonin replacement therapy in patients with FM and CFS.
J Rheumatol
1999 Dec;
26(12):2675-80
Lentz MJ, Landis CA, Rothermel J, Shaver JL
Effects of selective slow wave sleep disruption on musculoskeletal pain
and fatigue in middle-aged women
OBJECTIVE: To
determine whether disrupted slow wave sleep (SWS)
would evoke
musculoskeletal pain, fatigue, and an alpha electroencephalograph (EEG) sleep pattern. We
selectively deprived 12 healthy, middle-aged, sedentary women without muscle
discomfort of SWS for 3 consecutive nights. Effects were assessed for the
following measures: polysomnographic sleep, musculoskeletal tender point pain
threshold, skinfold tenderness, reactive hyperemia (inflammatory flare
response), somatic symptoms, and mood state. METHODS: Sleep was recorded and scored using standard
methods. On selective SWS deprivation (SWSD) nights, when delta waves
(indicative of SWS)
were detected
on EEG, a computer-generated tone
(maximum 85 decibels) was delivered until delta waves disappeared.
Musculoskeletal tender points were measured by dolorimetry; skinfold tenderness
was assessed by skin roll procedure; and reactive hyperemia was assessed with
a cotton swab test. Subjects completed questionnaires on bodily feelings,
symptoms, and mood. RESULTS: On
each SWSD night, SWS was decreased significantly
with minimal alterations in total sleep time, sleep efficiency, and other sleep
stages. Subjects showed a 24% decrease in musculoskeletal pain threshold after
the third SWSD night. They also reported
increased discomfort, tiredness, fatigue, and reduced vigor. The flare
response (area of vasodilatation) in skin was greater than baseline after the
first, and again, after the third SWSD night. However, the automated program for SWSD did not evoke an alpha EEG sleep pattern. CONCLUSION: Disrupting SWS, without reducing total sleep
or sleep efficiency, for several consecutive nights is associated with
decreased pain threshold, increased discomfort, fatigue, and the inflammatory
flare response in skin. These results suggest that disrupted sleep is probably
an important factor in the pathophysiology of symptoms in fibromyalgia.
J Rheumatol
1999 Jul; 26(7): 1586-92
Maes M, Libbrecht I, Van Hunsel F, Lin AH, De Clerck L, Stevens W, Kenis G, de Jongh R, Bosmans E, Neels H
Fibromyalgia is a chronic, painful musculoskeletal disorder
characterized by widespread pain, pressure hyperalgesia, morning stiffness and
by an increased incidence of depressive symptoms. The etiology, however, has
remained elusive. The aim of the present study was to examine the inflammatory
response system (IRS)
in
fibromyalgia. Serum
interleukin-6 (IL-6),
soluble IL-6 receptor (sIL-6R), sgp130, sIL-IR antagonist (IL-1RA) and sCD8
were determined in 33 healthy volunteers and in 21 fibromyalgia patients,
classified according to the American College of Rheumatology criteria. Severity
of illness was measured with several pain scales, dolorimetry and the Hamilton
Depression Rating Scale (HDRS). Serum
sgp130 was significantly higher and serum sCD8 significantly lower in
fibromyalgia patients than in healthy volunteers. Serum sIL-6R and sIL-1RA were significantly higher in
fibromyalgia patients with an increased HDRS score (>or =16)
than in normal volunteers and fibromyalgia patients with a HDRS score < 16. In fibromyalgia
patients, an important part of the variance in sCD8 (50.3%) and IL-1RA (19.3%) could be explained
by the HDRS score; 74.3% of the variance
in sIL-6R was explained by the
combined effects of pain symptoms and the HDRS score; and 25.9% of the variance in serum sgp13O was explained by
stiffness. The results support the contention that pain and stiffness in
fibromyalgia may be accompanied by a suppression of some aspects of the IRS and that the presence of
clinically significant depressive symptoms in fibromyalgia is associated with
some signs of IRS
activation.
Psychoneuroendocrinology 1999 May; 24(4): 371-83
Miller CS
Are we on the threshold of a new theory of disease? Toxicant-induced
loss of tolerance and its relationship to addiction and abdiction
Toxicant-induced loss of tolerance (or TILT) describes a two-step disease process in which (1)
certain chemical exposures, e.g., indoor air contaminants, chemical spills, or
pesticide applications, cause certain susceptible persons to lose their prior
natural tolerance for common chemicals, foods, and drugs (initiation); (2)
subsequently, previously tolerated exposures trigger symptoms. Responses may
manifest as addictive or abdictive (avoidant) behaviors. In some
affected individuals, overlapping responses to common chemical, food, and drug
exposures, as well as habituation to recurrent exposures, may hide (mask)
responses to particular triggers. Accumulating evidence suggests that this
disease process might underlie a broad array of medical illnesses including
chronic fatigue, fibromyalgia, migraine headaches, depression, asthma, the
unexplained illnesses of Gulf War veterans, multiple chemical sensitivity, and
attention deficit disorder.
Toxicol Ind Health 1999 Apr-Jun; 1 5(3-4):28-9
Neeck G, Riedel W
Hormonal perturbations in fibromyalgia syndrome
The symptomatology characterizing fibromyalgia (FM) comprises three
systems: the musculoskeletal system with widespread muscular pain, neuroendocrine
disorders, and psychological distress including depression. Though the most
prominent symptom of FM is
pain in defined points of the musculoskeletal system, the numerous other somatoform
and psychological disorders suppose a common primary disturbance which we
consider to originate within higher levels of the central nervous system.
Recent studies of the entire endocrine profile of FM patients following a
simultaneous challenge of the hypophysis with corticotropin-releasing hormone (CRH), thyrotropin-releasing
hormone, growth hormone-releasing hormone, and luteinizing hormone-releasing
hormone support the hypothesis that an elevated activity of CRH neurons
determines not only many symptoms of FM but may also cause the deviations observed in the other hormonal axes.
Hypothalamic CRH
neurons thus
may play a key role not only in “resetting” the various endocrine loops but
possibly also nociceptive and psychological mechanisms as well.
Ann NY Acad Sci 1999; Jun 22;876:325-38
Pennacchio EA, Borg-Stein J, Keith DA
The incidence of pain in the muscles of mastication in patients with
fibromyalgia
This study recognizes the high incidence of
temporomandibular symptoms in a group of patients with documented fibromyalgia.
Findings indicate that the diagnosis and treatment of temporomandibular
disorders and fibromyalgia have many similarities.
J Mass Dent Soc 1998 Fall; 47(3):8-12
Rossy LA, Buckelew SP, Dorr N, Hagglund KJ, Thayer JF, McIntosh MJ,
Hewett JE, Johnson JC
A meta-analysis of fibromyalgia treatment interventions
OBJECTIVE: To
evaluate and compare the efficacy of pharmacological and non-pharmacological
treatments of fibromyalgia syndrome (FMS). METHODS: This meta-analysis of 49
fibromyalgia treatment outcome studies assessed the efficacy of pharmacological
and non-pharmacological treatment across four types of outcome
measures—physical status, self-report of FMS symptoms, psychological status,
and daily functioning. RESULTS: After controlling for study design,
antidepressants resulted in improvements on physical status and self-report of
FMS symptoms. All non-pharmacological treatments were associated with
significant improvements in all four categories of outcome measures with the
exception that physically-based treatment (primarily exercise) did not
significantly improve daily functioning. When compared, non-pharmacological
treatment appears to be more efficacious in improving self-report of FMS symptoms than
pharmacological treatment alone. A similar trend was suggested for functional
measures. CONCLUSION:
The optimal
intervention for FMS
would include
non-pharmacological treatments, specifically exercise and cognitive-behavioral
therapy, in addition to appropriate medication management as needed for sleep
and pain symptoms.
Ann Behav Med 1999 Spring;2l(2):180-91
Russell IJ
Is fibromyalgia a distinct clinical entity? The clinical investigator’s
evidence
SUBJECTIVE: Chronic widespread pain with multiple tender points (fibromyalgia
syndrome) is a common clinical presentation. Criteria for inclusion of
fibromyalgia patients into research studies have led to a medical model which
integrates symptoms, signs, epidemiology, pathogenesis, responses to treatment,
and prognosis. Controversy regarding fibromyalgia relates mostly to issues of
compensation. THEORETICAL:
The diagnosis
of fibromyalgia has been challenged as an inappropriate extraction from an
epidemiological continuum of subjective discomfort. However, there are many
conditions in which normally distributed measures exhibit distinctly unique
outcomes at their extremes. OBJECTIVE: Since
fibromyalgia patients exhibit lowered pain thresholds, the process of
nociception was studied. Samples of fibromyalgia urine, blood, and spinal fluid
disclosed abnormalities consistent with a biomedical model of failed
neuroregulatory inhibition, altered nociception, central sensitization, and
allodynia. All three views support fibromyalgia as a distinct clinical syndrome
deserving of informed medical care and continued research to better
understand chronic widespread pain.
Baillieres Best Pract Res Clin Rheumatol 1999 Sep; 13(3):445-54
Russell IJ, Michalek JE, Kang YK, Richards AB
Reduction of morning stiffness and improvement in physical function in
fibromyalgia syndrome patients treated sublingually with low doses of human
interferon-alpha
One hundred and twelve fibromyalgia syndrome (FMS) patients were randomized
into one of four demographically similar groups (N=28/group). Sequential
primary FMS patient volunteers were to
receive daily sublingual placebo or interferon-alpha (IFN-alpha) at 15, 50, or
150 IU. After a screening
evaluation, analgesic or sedative hypnotic medications were withdrawn. Two
weeks later, daily IFN-alpha or placebo was initiated with follow-up
evaluations at 2-week intervals ending with week 6. One primary, three
secondary, and seven tertiary variables were assessed. Study outcome was based
on improvement in the tender point index (TPI). The TPI did not improve with any IFN-alpha dose.
However, significant improvement was seen in morning stiffness and in physical
function with the 50 IU IFN-alpha
(p<0.01). None of the other outcome means changed significantly and
no adverse events were attributable to IFN-alpha therapy.
J lnterferon Cytokine Res 1999 Aug; 19(8):96-8
Russell IJ, Vipraio GA, Michalek JE, Craig FE, Kang YK, Richards AB
Lymphocyte markers and natural killer cell activity in fibromyalgia
syndrome: effects of low-dose, sublingual use of human interferon-alpha
A clinical study was designed to utilize flow cytometric
immunophenotyping and chromium release from cultured tumor target cells to
characterize peripheral blood mononuclear leukocyte (PBML) subpopulations and natural
killer activity in healthy normal controls (N=18) and in patients with fibromyalgia
syndrome (FMS) at baseline (N= 124) and again after 6 weeks
of treatment with low doses of orally administered human interferon-alpha
(IFN-alpha). Volunteer subjects discontinued all analgesic and sedative
hypnotic medications for 2 weeks prior to the baseline phlebotomy. Laboratory
measures included a complete blood count; a phenotypic analysis of PBML by flow cytometry; and in
vitro natural killer (NK) cell
activity. After baseline blood sample collection, the FMS patients were randomized to
one of four parallel treatment groups (N=28/group) to receive sublingual IFN-alpha (15 IU, 50 IU, 150 IU), or placebo every morning for
6 weeks. The tests were repeated at week 6 to evaluate treatment effects. At
baseline, FMS patients exhibited fewer
lymphocytes and more CD25+ T lymphocytes
than did normal controls. By week 6, the main significant and consistent change
was a decrease in the HLA-DR+ CD4+
subpopulation
in the 15 IU and 150 IU treatment groups. These data
do not support an immunologically dysfunctional PBML phenotype among patients with FMS as has been observed in the
chronic fatigue syndrome.
J lnterferon Cytokine Res 1999 Aug; 19(8):969-78
Schwarz MJ, Spath M, Muller-Bardorff H, Pongratz DE, Bondy B, Ackenheil
M
Relationship of substance P, 5-hydroxyindole acetic acid and tryptophan
in serum of fibromyalgia patients
The serotonergic system has repeatedly been discussed to be involved in
the pathophysiology of fibromyalgia (FM), which is a syndrome of widespread pain and sleep
disturbance. Elevated levels of substance P (SP), a mediator of nociception, have been described in FM. In this study the possible relationship
between SP and serotonin (5-HT) together with its precursor
tryptophan (TRP)
and its
metabolite 5-hydroxyindoleacetic acid (5-HIAA) was evaluated in 51 serum samples of fibromyalgia
patients. These parameters were compared with clinical data such as pain
intensity or sleep quality. A strong negative correlation between SP and 5-HIAA
(p=.000) as
well as between SP
and TRP (p=.009) could be demonstrated.
High serum concentrations of 5-HIAA and
TRP showed a significant
relation to low pain scores (5-HIAA: p=.030;
TRP: p=.014). Moreover, 5-HIAA was strongly related to good
quality of sleep (p=.000), while SP was related to sleep
disturbance (p=.005). These data are valid to support the hypothesis of a
systemic involvement of 5-HT and
SP in fibromyalgia.
Neurosci Lett 1999 Jan 15; 259(3):196-8
Sprott H, Muller A, Heine H
OBJECTIVE: The
acceptance of fibromyalgia as a disease entity and its definitive diagnosis
have been hampered by a dearth of knowledge concerning the underlying
pathophysiology of this disease and the lack of specific biochemical markers
applicable to its diagnosis. To determine whether abnormal collagen metabolism
is a characteristic of fibromyalgia, we have analyzed collagen metabolites in
the urine and serum of patients with fibromyalgia. METHODS: The diagnosis of
fibromyalgia was made according to the American College of Rheumatology
criteria. Urine and serum were collected under standardized conditions from 39
patients and 55 age- and sex-matched controls. Pyridinoline (Pyd) and deoxypyridinoline
(Dpyd), which represent products of lysyl oxidase-mediated cross-linking in
collagen and are indicators of connective tissue and bone degradation,
respectively, were analyzed by ion-paired and gradient HPLC method with fluorescence
detection (HPLC).
Levels of
hydroxypyroline (Hyp), a collagen turnover marker, were also measured. The
findings were related to creatinine levels and the Pyd/Dpyd ratio determined. RESULTS: The Pyd/Dpyd ratios in the
urine and serum and the Hyp in the urine were significantly lower in patients
with fibromyalgia than in healthy controls. CONCLUSION: Decreased levels of collagen cross-linking
may contribute to remodeling of the extracellular matrix and collagen deposition
around the nerve fibers in fibromyalgia and contribute to the lower pain
threshold at the tender points. Analysis of altered collagen metabolism either
by histologic examination on biopsy or, preferably, by HPLC analysis of collagen
metabolites in urine or serum may aid in understanding more about the pathogenesis
of fibromyalgia.
Z Rheumatol 1998; 57 Suppl 2:52-5
Tougas G
Communications along the brain-gut axis
involve neural pathways as well as immune and endocrine mechanisms. The two
branches of the autonomic nervous system are integrated anatomically and
functionally with visceral sensory pathways, and are responsible for the
homeostatic regulation of gut function. The autonomic nervous system is also a
major mediator of the visceral response to central influences such as
psychological stress. As defined, functional disorders comprise a constellation
of symptoms, some of which suggest the presence of altered perception, while
other symptoms point to disordered gastrointestinal function as the cause of
the symptoms. A growing number of reports have demonstrated disordered
autonomic function in subgroups of functional bowel patients. While a number of
different methods were used to assess autonomic function, the reports point to
a generally decreased vagal (parasympathetic) outflow or increased sympathetic
activity in conditions usually associated with slow or decreased gastrointestinal
motility, while other studies found either an increased cholinergic activity or
a decreased sympathetic activity in patients with symptoms compatible with an
increased motor activity. Under certain conditions, altered autonomic balance
(including low vagal tone and increased sympathetic activity) may alter
visceral perception. Autonomic dysfunction may also represent the physiological
pathway accounting for many of the extraintestinal symptoms seen in irritable
bowel syndrome patients and some of the frequent gastrointestinal complaints
reported by patients with disorders such as chronic fatigue and fibromyalgia.
Can J Gastroenterol 1999 Mar; 13 Suppl A: 15A-17A
White KP,
Speechley M, Harth M, Ostbye T
The London
Fibromyalgia Epidemiology Study: comparing the demographic and clinical
characteristics in 100 random community cases of fibromyalgia versus controls
OBJECTIVE:
To identify demographic and clinical features that distinguish fibromyalgia
(FM) from other chronic widespread pain. METHODS: We identified 100 confirmed
FM cases, 76 widespread pain controls, and 135 general controls in a random
community survey of 3395 noninstitutionalized adults living in London, Ontario
[Canada]. FM cases were distinguished from pain controls using the 1990
American College of Rheumatology (ACR) classification criteria for FM. RESULTS:
The mean age of FM cases was 47.8 years (range 19 to 86), the same as for pain
controls; 86% of FM cases were female versus 67.1 % of pain controls
(p<0.01). . . Male and female FM cases were similar, except females were
older and reported more major symptoms (both p=0.02). FM cases reported more
severe pain and fatigue, more symptoms, more major symptoms, and worse overall
health than pain controls or general controls. The most commonly reported major
symptoms among FM cases were musculoskeletal pain (77.3%), fatigue (77.3%),
severe fatigue lasting 24 h after minimal activity (77.0%), non-restorative
sleep (65.7%), and insomnia (56.0%). Subjects with 11-14 tender points were
more similar to those with 15-18 tender points than to those with 7-10 points
in 11 of 14 clinical variables. On multivariate analysis, 4 symptoms
distinguished FM cases from pain controls: pain severity (p=0.004), severe
fatigue lasting 24 h after minimal activity (p=0.006), weakness (p=0.008), and
self-reported swelling of neck glands (p=0.01). CONCLUSION: In the general
population, adults who meet the ACR definition of FM appear to have distinct
features compared to those with chronic widespread pain who do not meet
criteria.
J Rheumatol 1999 Jul; 26(7):1577-85
White KP,
Speechley M, Harth M, Ostbye T
The London
Fibromyalgia Epidemiology Study: the prevalence of fibromyalgia syndrome in
London, Ontario
OBJECTIVE:
To estimate the prevalence of fibromyalgia syndrome (FM) among
non-institutionalized Canadian adults; and to assess the effect of demographic
variables on the odds of having FM. METHODS: A screening questionnaire was
administered via telephone to a random community sample of 3395
noninstitutionalized adults residing in London, Ontario [Canada]. Individuals
screening positive were invited to be examined by a rheumatologist to confirm
or exclude FM using the 1990 American College of Rheumatology classification
criteria. RESULTS: One hundred confirmed cases of FM were identifed, of whom 86
were women. Mean age among FM cases was 49.2 years among women, 39.3 years
among men (p<0.02). FM affects an estimated 4.9% (95% CI 4.7%, 5.1%) of
adult women and 1.6%(1.3%,1.9%) of adult men in London, for a female to male
ratio of roughly 3:1. In women, prevalence rises steadily with age from <1%
in women aged 18-30 to almost 8% in women 55-64. Thereafter, it declines. The
peak prevalence in men also appears to be in middle age (2.5%; 1.1 %, 5.7%). FM
affects 3.3% (3.2%, 3.4%) of noninstitutionalized adults in London. Female sex,
middle age, less education, lower household income, being divorced, and being
disabled are associated with increased odds of having FM. CONCLUSION: FM is a
common musculoskeletal disorder among Canadian adults, especially among women
and persons of lower socioeconomic status.
J Rheumatol 1999 Jul; 26(7):1570-6
Wilson RB,
Gluck OS, Tesser JR, Rice JC, Meyer A, Bridges AJ
Antipolymer
antibody reactivity in a subset of patients with fibromyalgia correlates with
severity
OBJECTIVE:
To determine the prevalence of antipolymer antibodies (APA) in patients with
fibromyalgia (FM) and autoimmune disease control groups and to determine if the
presence of these antibodies correlates with severity in patients with FM.
METHODS: Sera from patients with FM (N=47), osteoarthritis (OA) (N= 16), and
rheumatoid arthritis (RA) (N= 13) were analyzed. Patients with im-
plants of
any kind and patients with concurrent autoimmune conditions were excluded from
study. Banked sera from autoimmune disease controls including poly/dermatomyosis
(N= 15), RA (N=30), systemic lupus erythematosus (SLE) (N=30), and systemic
sclerosis (SSc) (N=30) were also analyzed. To determine if seroreactivity
correlates with severity, banked sera from patients with FM assessed as severe
(N=28) or mild (N=37) and from controls (N=21) were assayed. RESULTS:
Following analysis, the prevalence of seroreactivity was
found to be higher in patients with FM (22/47,
47%) compared to patients with OA (3/16,
19%; p<0.1) or RA (1/13, 8%; p<0.05)
and the autoimmune disease control sera from poly/dermatomyosis (2/15, 13%;
p<0.05), and patients with RA (3/30, 10%;
p<0.01), SLE (1/30, 3%; p<0.01),
and SSc (1/30, 3%; p< 0.01).
The prevalence of APA seroreactivity was
also significantly higher in patients with severe FM
(17/28, 61%) compared to patients with mild FM
(11/37, 30%; p <0.05)
and controls (4/21, 19%; p<0.01). In addition,
both mean threshold and mean tolerance dolorimetry scores were significantly
lower in the seropositive patients with mild FM (1.33+/-
0.21, 1.95 +/- 0.25, respectively) compared to the seronegative patients
(1.83+/-0.08, 2.53 +/-0.11; p<0.05 for both comparisons, respectively). CONCLUSION:
These results reveal that an immunological response,
production of anti-polymer antibodies, is associated with a subset of patients
with FM. The results also suggest that the APA
assay may be an objective marker in the diagnosis and
assessment of FM and may provide
additional avenues of investigation into the pathophysiological processes
involved in FM.
J Rheumatol 1999
Feb; 26(2):40-7
Wolfe F, Anderson J
Silicone filled breast implants and the risk of fibromyalgia and
rheumatoid arthritis
OBJECTIVE: The symptoms of what has been called silicone implant
associated syndrome (SIAS) and
fibromyalgia (FM) are similar. It
has been hypothesized that silicone (filled) breast implants (SBI) might be causally related to the
development of FM. This
hypothesis was investigated by comparing 508 patients with FM with 1228 control subjects. We also
studied the relationship of SBI to
the subsequent development of rheumatoid arthritis (RA). METHODS: Utilizing a longitudinal data bank, implantation
status was determined in 464 patients with RA, 508 with FM, 261
with osteoarthritis (OA) of the
knee or hip, and in 503 randomly selected community controls. We obtained data
on the type of implant and its temporal relationship to the onset of FM and RA. RESULTS: No association between SBI and RA was
found (OR 1.66, 95% CI 0.33, 8.23, p=0.538). No association
between prior SBI and subsequent FM was found (OR 1.22, 95% CI 0.30,
4.89, p=0.781). But one-third of the SBI
in FM occurred after
development of the syndrome. When all implants regardless of temporal relationship
were considered, the overall relationship between any implant and the diagnosis
of FM was significant at p=0.095 (OR 2.45, 95% CI 0.86, 7.03). CONCLUSION:
No relationship between prior SBI
and the subsequent development of FM
or RA was noted. But
implants appear to be more common in
patients with than in those without FM (p= 0.095). A common, predisposing set of
psychosocial characteristics may be shared between those who have FM and those who undergo SBI.
J Rheumatol 1999
Sep; 26(9):2025-8
Yunus MB, Khan MA, Rawlings KK, Green JR, Olson JM, Shah S
Genetic linkage analysis of multicase families with fibromyalgia
syndrome
OBJECTIVE: Based on the reports of familial aggregation of fibromyalgia (FM) syndrome, we investigated its possible genetic linkage to HLA by studying multicase families. METHODS: Forty Caucasian multicase families with a diagnosis of FM (American College of Rheumatology criteria) in 2 or more first degree relatives were investigated. Eighty-five affected and 21 unaffected members of 41 sibships were studied. Depression symptomology was assessed by Zung Self-rating Depression Scale (SDS). HLA typing was performed for A, B, and DRB 1 alleles, and haplotypes were determined with no knowledge of the subject’s diagnosis. We investigated genetic linkage to the HLA region by evaluating sibships in multicase families. RESULTS: Sibship analysis showed significant genetic linkage of FM to the HLA region (p=0.028). Subgroup analysis was also performed for 17 families where the proband was also noted to have depression (with an SDS index value > or = 60). We found that the presence of depression did not influence the observed results (p=0.22). CONCLUSION: Our study of 40 multicase families confirms the existence of a possible gene for FM that is linked with the HLA region. Our results should be regarded as preliminary and their independent confirmation by other studies is warranted.
J Rheumatol 1999 Feb; 26(2):408-12